Global and Low-Resource Perspectives on ME/CFS

1 Arron et al. 2024 — ME/CFS as a Neglected Disease

(Arron2024neglectedDisease?)

Full Citation:: Arron HE, Marsh BD, Kell DB, Khan MA, Jaeger BR, Pretorius E. Myalgic Encephalomyelitis/Chronic Fatigue Syndrome: the biology of a neglected disease. Frontiers in Immunology. 2024;15:1386607. DOI:: 10.3389/fimmu.2024.1386607 PMID:: 38887284 PMCID:: PMC11180809 Study Design:: Narrative review Key Findings::

  • Characterises ME/CFS as a “neglected disease” with biological basis centred on microclots and amyloid fibrin

  • Co-author Pretorius is based in South Africa — one of few ME/CFS research contributions from the African continent

  • Argues that ME/CFS research is concentrated in high-income countries, creating a global evidence gap Conclusion:: ME/CFS meets criteria for a neglected disease in global health; biological mechanisms (microclots) provide testable targets. Limitations:: Narrative review; Pretorius group’s microclot hypothesis is controversial; no primary data. Certainty Assessment::

  • Quality: Medium (Frontiers in Immunology, narrative review)

  • Sample: N/A (review)

  • Replication: N/A

  • Score: 0.65 Study Date Era:: Post-IOM 2015–present

2 Condé et al. 2026 — Post-Dengue Fatigue Systematic Review and Meta-Analysis

(Conde2026dengueFatigue?)

Full Citation:: Condé A, Maillard O, Rodrigo C, Bertolotti A, Sandler CX, Lloyd AR, Gérardin P. Post-Infectious Fatigue and Depression Following Dengue: A Systematic Review and Meta-Analysis of Associated Factors. Reviews in Medical Virology. 2026;36(3):e70164. DOI:: 10.1002/rmv.70164 Study Design:: Systematic review and meta-analysis Key Findings::

  • First systematic review quantifying post-dengue fatigue

  • Dengue endemic in 100+ countries, predominantly LMICs

  • Post-infectious fatigue prevalence and associated factors systematically assessed

  • Establishes that arboviral infections in LMICs produce chronic fatigue syndromes comparable to post-EBV CFS Conclusion:: Post-dengue fatigue is a significant public health burden in dengue-endemic LMICs, largely unrecognized as a post-infectious fatigue syndrome. Limitations:: Heterogeneity in fatigue definitions across studies; limited number of eligible studies; no ME/CFS diagnostic criteria applied. Certainty Assessment::

  • Quality: Medium-High (Reviews in Medical Virology, systematic review with meta-analysis)

  • Sample: Systematic review of published studies

  • Replication: First systematic review of this question

  • Score: 0.75 Study Date Era:: Post-IOM 2015–present

3 Duvignaud et al. 2018 — Post-Chikungunya Chronic Fatigue (TELECHIK Cohort)

(Duvignaud2018chikungunyaFatigue?)

Full Citation:: Duvignaud A, Fianu A, Bertolotti A, et al. Rheumatism and chronic fatigue, the two facets of post-chikungunya disease: the TELECHIK cohort study on Reunion island. Epidemiology and Infection. 2018;146(5):633–641. DOI:: 10.1017/S0950268818000031 PMID:: 29486812 PMCID:: PMC5892425 Study Design:: Prospective cohort study Sample Size:: Reunion Island chikungunya outbreak survivors followed over 30 months Key Findings::

  • Two major post-chikungunya sequelae: chronic rheumatism and chronic fatigue

  • Chronic fatigue affected substantial proportion at long-term follow-up

  • Demonstrates post-arboviral fatigue as major public health burden in tropical settings Conclusion:: Post-chikungunya chronic fatigue mirrors post-infectious CFS — supports arboviral infections as ME/CFS triggers in tropical LMIC settings. Limitations:: Single outbreak setting; no ME/CFS diagnostic criteria applied; tropical island (Reunion is French overseas department, not typical LMIC). Certainty Assessment::

  • Quality: Medium (Epidemiology and Infection, prospective cohort)

  • Sample: Moderate cohort size

  • Replication: Single cohort at Reunion Island

  • Score: 0.70 Study Date Era:: CCC/ICC 2003–2015

4 Vester et al. 2026 — Burden of Disease Scoping Review

(Vester2026burdenOfDisease?)

Full Citation:: Vester P, Boudouroglou-Walter S, Schreyögg J, Wieting C, Blome C. Burden of Disease in Myalgic Encephalomyelitis/Chronic Fatigue Syndrome (ME/CFS): A Scoping Review. Applied Health Economics and Health Policy. 2026;24(1):147–161. DOI:: 10.1007/s40258-025-01006-2 PMID:: 40986167 PMCID:: PMC12790524 Study Design:: Scoping review Key Findings::

  • Consistent severe QoL impairment in ME/CFS (EQ-5D scores ~0.40–0.55, lower than MS/stroke)

  • Economic burden estimated at $18–51B in the US

  • No non-high-income-country burden estimates identified in the review

  • Gap: burden of disease data entirely absent from LMICs Conclusion:: ME/CFS imposes severe disease burden comparable to major chronic diseases; global data gap on LMIC burden is a critical evidence void. Limitations:: Scoping review, not systematic; heterogeneity in burden measures; high-income country data only. Certainty Assessment::

  • Quality: Medium (Applied Health Economics and Health Policy, systematic search)

  • Sample: Scoping review of published studies

  • Replication: First scoping review of ME/CFS disease burden

  • Score: 0.60 Study Date Era:: Post-IOM 2015–present

5 Sarker et al. 2024 — Bangladesh ME/CFS RCT Protocol

(Sarker2024bangladeshRCTprotocol?)

Full Citation:: Sarker AH, Hossain KMA, Kabir MF, et al. Comparing effectiveness of physiotherapy versus drug management on fatigue, physical functioning, and episodic disability for myalgic encephalomyelitis in post-COVID-19 condition: a study protocol of randomized control trial. Trials. 2024;25(1):321. DOI:: 10.1186/s13063-024-08077-x PMID:: 38750586 PMCID:: PMC11094988 Study Design:: Published RCT protocol Sample Size:: Planned RCT from Bangladesh Key Findings::

  • First registered ME/CFS clinical trial from Bangladesh

  • Testing physiotherapy vs drug management in post-COVID ME

  • Uses episodic disability framework relevant to LMIC settings where continuous disability assessments are impractical

  • Represents emerging ME/CFS research capacity in South Asia Conclusion:: LMIC ME/CFS research is emerging, led by post-COVID clinical needs in Bangladesh. Limitations:: Protocol only — no efficacy data; Fukuda criteria applied; physiotherapy approach may be contraindicated in PEM+ patients. Certainty Assessment::

  • Quality: Medium (Trials journal, pre-registered RCT)

  • Sample: Planned, not yet reported

  • Replication: N/A (protocol)

  • Score: 0.50 Study Date Era:: Post-IOM 2015–present

6 Starcevic 1999 — Neurasthenia and Chronic Fatigue Syndrome

(Starcevic1999neurasthenia?)

Full Citation:: Starcevic V. Neurasthenia: cross-cultural and conceptual issues in relation to chronic fatigue syndrome. General Hospital Psychiatry. 1999;21(4):249–255. DOI:: 10.1016/S0163-8343(99)00012-2 PMID:: 10514948 Study Design:: Comparative review Key Findings::

  • Maps conceptual relationship between neurasthenia (ICD-10) and CFS

  • Notes that neurasthenia remains prevalent diagnosis in China, East Asia, and parts of Eastern Europe

  • Global diagnostic expansion eliminates neurasthenia as label in some settings while CFS/ME emerge as functional replacement

  • Cultural framing determines whether fatigue is reported as psychological or somatic Conclusion:: CFS and neurasthenia are overlapping but culturally-moderated constructs; diagnostic labelling is shaped by local medical culture, not biology alone. Limitations:: 1999-era conceptual review; limited empirical data; pre-IOM diagnostic era. Certainty Assessment::

  • Quality: Medium (General Hospital Psychiatry, narrative review)

  • Sample: N/A

  • Replication: Cross-cultural comparisons consistent with Lee, Ware/Kleinman

  • Score: 0.50 Study Date Era:: Fukuda 1994–2003

7 Ware and Kleinman 1992 — Culture and Somatic Experience

(Ware1992cultureSomatic?)

Full Citation:: Ware NC, Kleinman A. Culture and somatic experience: the social course of illness in neurasthenia and chronic fatigue syndrome. Psychosomatic Medicine. 1992;54(5):546–560. DOI:: 10.1097/00006842-199209000-00003 PMID:: 1438658 Study Design:: Comparative anthropological analysis (China vs US) Key Findings::

  • Landmark cross-cultural comparison of neurasthenia in China and CFS in the United States

  • Different cultural idioms for similar fatigue syndromes — somatic idioms dominant in China, psychological in US

  • Social course of illness shaped by cultural norms about illness behaviour and legitimacy

  • Demonstrates that “the same” illness can present differently depending on cultural context Conclusion:: ME/CFS symptom expression is culturally moderated — global prevalence estimates using Western diagnostic criteria may misclassify cases in non-Western settings. Limitations:: Pre-Fukuda era; small qualitative samples; China vs US only (does not cover Africa, South Asia, Latin America). Certainty Assessment::

  • Quality: High (Psychosomatic Medicine, Arthur Kleinman — leading medical anthropologist)

  • Sample: Qualitative, small

  • Replication: Consistent with Lee 1995, 1998, 2000

  • Score: 0.55 Study Date Era:: Pre-1994

8 Lee 1998 — Neurasthenia in Contemporary Chinese Society

(Lee1998neurastheniaChina?)

Full Citation:: Lee S. Estranged bodies, simulated harmony, and misplaced cultures: neurasthenia in contemporary Chinese society. Psychosomatic Medicine. 1998;60(4):448–457. DOI:: 10.1097/00006842-199807000-00010 PMID:: 9710290 Study Design:: Ethnographic and clinical review Key Findings::

  • Shenjing shuairuo (neurasthenia) remains culturally acceptable idiom for fatigue/distress in Chinese society

  • ME/CFS would be filtered through this culturally shaped lens if assessed with Western instruments

  • Body-centred distress expression reflects social norms about legitimate illness, not lack of psychological insight

  • Western diagnostic expansion (CFS, depression, anxiety) has partially displaced neurasthenia in urban/professional Chinese populations Conclusion:: CFS-like conditions in China are labelled neurasthenia; direct application of Fukuda/CCC criteria would produce artefactually low prevalence. Limitations:: Single-culture focus (Chinese); 1998 data may not reflect contemporary urbanisation effects. Certainty Assessment::

  • Quality: Medium (Psychosomatic Medicine, clinical-anthropological review)

  • Sample: N/A

  • Replication: Consistent with Ware/Kleinman 1992, Lee 2000

  • Score: 0.50 Study Date Era:: Pre-Fukuda / early Fukuda 1994–2003

9 National Academies 2024 — Common Research Agenda for Infection-Associated Chronic Illnesses

(NationalAcademies2024researchAgenda?)

Full Citation:: National Academies of Sciences, Engineering, and Medicine. Toward a Common Research Agenda in Infection-Associated Chronic Illnesses: Proceedings of a Workshop. Washington, DC: National Academies Press; 2024. DOI:: 10.17226/27462 PMID:: 38648305 Study Design:: Workshop proceedings Key Findings::

  • Convened experts across ME/CFS, Long COVID, post-Lyme, and other infection-associated chronic illnesses (IACI)

  • Called for common research frameworks, shared biomarkers, and international standardization

  • Global health dimension present but underdeveloped — LMIC perspectives largely absent from workshop

  • Identified cross-disease mechanisms: immune dysregulation, autonomic dysfunction, neuroinflammation Conclusion:: First major institutional effort to unify post-infectious fatigue research; LMIC engagement a recognised gap. Limitations:: US-centric workshop; LMIC representation minimal; proceedings, not peer-reviewed research. Certainty Assessment::

  • Quality: High (National Academies institutional authority)

  • Sample: Workshop with expert panels

  • Replication: N/A

  • Score: 0.70 Study Date Era:: Post-IOM 2015–present

10 Podell et al. 2020 — Documenting Disability in ME/CFS

(Podell2020documentingDisability?)

Full Citation:: Podell R, Dimmock ME, Comerford BB. Documenting disability in Myalgic Encephalomyelitis/Chronic Fatigue Syndrome (ME/CFS). Work. 2020;66(2):339–352. DOI:: 10.3233/WOR-203178 PMID:: 32568153 Study Design:: Practical guidance / review Key Findings::

  • Practical framework for documenting ME/CFS functional impairment for disability claims

  • ME/CFS coded as G93.3 in ICD-10, 8E49 in ICD-11

  • Highlights disconnect between ICD coding existence and practical disability recognition

  • Relevant to LMIC settings where disability insurance systems are weak or absent — functional documentation can support claims in any system Conclusion:: Existence of ICD codes for ME/CFS does not guarantee disability recognition; documentation standards matter. Limitations:: US-centric legal/insurance framework; not specific to LMIC contexts. Certainty Assessment::

  • Quality: Medium (Work journal, expert guidance)

  • Sample: N/A

  • Replication: N/A

  • Score: 0.65 Study Date Era:: CCC/ICC 2003–2015

11 Simani et al. 2021 — Post-COVID CFS Prevalence in Iran

(Simani2021iranCFS?)

Full Citation:: Simani L, Ramezani M, Darazam IA, Sagharichi M, Aalipour MA, Ghorbani F, Pakdaman H. Prevalence and correlates of chronic fatigue syndrome and post-traumatic stress disorder after the outbreak of the COVID-19. Journal of Neurovirology. 2021;27(1):154–159. DOI:: 10.1007/s13365-021-00949-1 PMID:: 33528827 PMCID:: PMC7852482 Study Design:: Cross-sectional prevalence study Sample Size:: Hospitalised COVID-19 patients in Tehran, Iran Key Findings::

  • 17.5% of hospitalised COVID-19 patients met Fukuda CFS criteria at 6-month follow-up

  • 75% of CFS cases were female

  • First ME/CFS prevalence estimate from a middle-income Middle Eastern country

  • Post-infectious CFS in an LMIC mirrors patterns seen in high-income countries Conclusion:: Post-infectious ME/CFS prevalence in Iran is comparable to estimates from HICs; ME/CFS burden in middle-income settings is real but under-measured. Limitations:: Hospital-based sample (severe COVID); Fukuda criteria only; no baseline fatigue assessment; single centre; PTSD confounding. Certainty Assessment::

  • Quality: Medium (Journal of Neurovirology)

  • Sample: Moderate

  • Replication: Single centre in Iran

  • Score: 0.55 Study Date Era:: Post-IOM 2015–present

12 Miller et al. 2026 — Post-Acute Sequelae Across Epidemic History

(Miller2026epidemicsShadow?)

Full Citation:: Miller CM, Moen JK, Iwasaki A. The lingering shadow of epidemics: post-acute sequelae across history. Trends in Immunology. 2026;47(1):9–18. DOI:: 10.1016/j.it.2025.10.010 PMID:: 41350176 Study Design:: Historical review Key Findings::

  • Post-acute sequelae documented after influenza 1918, polio, Ebola, SARS, and COVID-19

  • Chronic fatigue is a common thread across post-epidemic syndromes

  • Pandemics produce long-term disability disproportionately in settings with poor acute care infrastructure

  • Global health relevance: post-infectious fatigue burden follows infectious disease burden geographically Conclusion:: Post-infectious fatigue syndromes are historically recurrent; LMICs with high infectious disease burden likely carry disproportionate post-infectious fatigue burden. Limitations:: Historical review, not empirical; does not quantify LMIC burden. Certainty Assessment::

  • Quality: Medium (Trends in Immunology, Iwasaki lab)

  • Sample: N/A (historical review)

  • Replication: N/A

  • Score: 0.55 Study Date Era:: Post-IOM 2015–present

13 Wang et al. 2014 — Traditional Chinese Medicine for CFS (Systematic Review)

(Wang2014tcmCFS?)

Full Citation:: Wang YY, Li XX, Liu JP, Luo H, Ma LX, Alraek T. Traditional Chinese medicine for chronic fatigue syndrome: a systematic review of randomized clinical trials. Complementary Therapies in Medicine. 2014;22(4):826–833. DOI:: 10.1016/j.ctim.2014.06.004 PMID:: 25146086 Study Design:: Systematic review of RCTs Sample Size:: 23 RCTs included (n=1,776 total) Key Findings::

  • TCM herbal formulations show signal for fatigue reduction compared to placebo or conventional treatment

  • Methodological quality of included trials generally low (high risk of bias, small samples)

  • Limited evidence precludes firm conclusions about specific TCM formulations

  • TCM widely available in East Asian healthcare systems — even modest efficacy has population-level relevance Conclusion:: TCM may benefit CFS patients but evidence quality is insufficient for guideline recommendations. Limitations:: High risk of bias in primary studies; heterogeneous interventions; small samples; 2014 search date (dated). Certainty Assessment::

  • Quality: Medium (Complementary Therapies in Medicine, Cochrane-style SR)

  • Sample: 23 RCTs, n=1,776

  • Replication: Consistent with subsequent TCM SRs

  • Score: 0.60 Study Date Era:: CCC/ICC 2003–2015

14 Kong et al. 2023 — TCM Mind-Body Exercises for CFS (Meta-Analysis)

(Kong2023tcmMindBody?)

Full Citation:: Kong L, Ren J, Fang S, et al. Effects of traditional Chinese mind-body exercises for patients with chronic fatigue syndrome: A systematic review and meta-analysis. Journal of Global Health. 2023;13:04157. DOI:: 10.7189/jogh.13.04157 PMID:: 37994837 PMCID:: PMC10666566 Study Design:: Systematic review and meta-analysis Key Findings::

  • Tai Chi, Qigong, Baduanjin evaluated across multiple RCTs

  • Moderate effect size on fatigue reduction

  • Mind-body exercises accessible in LMIC settings where pharmacological options are limited

  • No serious adverse events reported Conclusion:: TCM mind-body exercises are safe and moderately effective for CFS fatigue; relevant to LMICs where these practices are culturally embedded and low-cost. Limitations:: Moderate heterogeneity; most studies from China (generalizability to non-Chinese populations uncertain); unblinded (inherent to exercise interventions). Certainty Assessment::

  • Quality: Medium (Journal of Global Health)

  • Sample: Multiple RCTs pooled

  • Replication: Consistent with prior TCM exercise reviews

  • Score: 0.65 Study Date Era:: Post-IOM 2015–present

15 Wang et al. 2017 — Acupuncture and Moxibustion for CFS (Network Meta-Analysis)

(Wang2017acupunctureCFS?)

Full Citation:: Wang T, Xu C, Pan K, Xiong H. Acupuncture and moxibustion for chronic fatigue syndrome in traditional Chinese medicine: a systematic review and meta-analysis. BMC Complementary and Alternative Medicine. 2017;17(1):163. DOI:: 10.1186/s12906-017-1647-x PMID:: 28335756 PMCID:: PMC5363012 Study Design:: Systematic review and network meta-analysis Sample Size:: 31 RCTs Key Findings::

  • Acupuncture and moxibustion show small-to-moderate effect on CFS fatigue

  • Acupuncture widely available in East Asian settings and increasingly in Indian traditional medicine contexts

  • Moxibustion (heat application at acupoints) also showed benefit

  • Network meta-analysis allowed indirect comparisons between modalities Conclusion:: Acupuncture is a moderately effective, low-risk option for CFS in settings where it is available and culturally accepted. Limitations:: Sham acupuncture controls difficult to blind; most studies from China; heterogeneity in acupuncture protocols. Certainty Assessment::

  • Quality: Medium (BMC CAM, now BMC Complementary Medicine and Therapies)

  • Sample: 31 RCTs

  • Replication: Consistent across TCM modality reviews

  • Score: 0.60 Study Date Era:: CCC/ICC 2003–2015